FIREFISH

E561096

FIREFISH is a pivotal clinical trial evaluating the efficacy and safety of risdiplam in infants with Type 1 spinal muscular atrophy.

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Observed surface forms (2)

Surface form Occurrences
FIREFISH Part 1 0
FIREFISH Part 2 0

Statements (47)

Predicate Object
instanceOf clinical trial
confirmatory efficacy and safety study
dose-finding study
pivotal trial
assessesOutcomeMeasure Children’s Hospital of Philadelphia Infant Test of Neuromuscular Disorders NERFINISHED
Hammersmith Infant Neurological Examination Section 2 NERFINISHED
overall survival
ventilation-free survival
developedWith PTC Therapeutics NERFINISHED
SMA Foundation NERFINISHED
enrollsAgeGroup infants aged 1 to 7 months at first dose
evaluates risdiplam
hasCondition 5q-associated spinal muscular atrophy Type 1
hasDesign multicenter
open-label
two-part study
hasGeographicScope international
hasInterventionModel single-group assignment
hasObjective determine the dose of risdiplam for Part 2
hasOutcome demonstrated clinically meaningful motor function improvement
demonstrated survival benefit compared with natural history
hasPart FIREFISH Part 1
FIREFISH Part 2 NERFINISHED
hasPhase Phase 2
hasPopulation infants with Type 1 spinal muscular atrophy
hasPrimaryEndpoint proportion of infants sitting without support
survival without permanent ventilation
hasPrimaryObjective evaluate efficacy of risdiplam in infants with Type 1 spinal muscular atrophy
hasPublicationType peer-reviewed clinical trial report
hasSecondaryObjective evaluate safety of risdiplam in infants with Type 1 spinal muscular atrophy
hasTherapeuticArea neuromuscular disease
rare disease
investigatesIndication Type 1 spinal muscular atrophy NERFINISHED
infantile-onset spinal muscular atrophy
monitorsSafetyParameters adverse events
laboratory abnormalities
ophthalmologic findings
relatedTo JEWELFISH clinical trial
RAINBOWFISH clinical trial
SUNFISH clinical trial NERFINISHED
sponsor F. Hoffmann-La Roche Ltd NERFINISHED
Roche NERFINISHED
studiesDrug risdiplam
supportsRegulatoryDecision approval of risdiplam for treatment of spinal muscular atrophy
targetsPathology survival motor neuron protein deficiency
usesDrugMechanism SMN2 pre-mRNA splicing modification by risdiplam
usesRouteOfAdministration oral administration of risdiplam

Referenced by (1)

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